Research Paper Volume 12, Issue 24 pp 24940—24956
Time gap between the onset and diagnosis in Werner syndrome: a nationwide survey and the 2020 registry in Japan
- 1 Department of Endocrinology, Hematology, and Gerontology, Chiba University Graduate School of Medicine, Chiba, Japan
- 2 Department of Diabetes and Metabolism, Asahi General Hospital, Asahi, Chiba, Japan
- 3 Department of Metabolic Medicine, Faculty of Life Sciences, Kumamoto University, Kumamoto, Japan
- 4 Department of Dermatology, Gunma University Graduate School of Medicine, Maebashi, Japan
- 5 Department of Health Development and Medicine, Osaka University Graduate School of Medicine, Osaka, Japan
- 6 Department of Medicine, Division of Diabetes, Metabolism and Endocrinology, Atami Hospital, International University of Health and Welfare, Atami, Japan
- 7 Department of Orthopaedic Surgery, Nara Medical University, Nara, Japan
- 8 Geriatric and General Medicine, Osaka University, Osaka, Japan
- 9 Department of Dermatology, Sumitomo Hospital, Osaka, Japan
- 10 Department of Diabetes and Endocrinology, Daini Osaka Police Hospital, Osaka, Japan
- 11 Diabetes and Endocrinology, Saga-Ken Medical Centre Koseikan, Saga, Japan
- 12 Department of Dermatology, Showa General Hospital, Tokyo, Japan
- 13 Department of Community Healthcare and Geriatrics, Nagoya University Graduate School of Medicine, Nagoya, Japan
- 14 Department of Medicine, Division of Diabetes, Metabolism and Endocrinology, International University of Health and Welfare, Narita, Japan
Received: October 14, 2020 Accepted: December 10, 2020 Published: December 29, 2020
https://doi.org/10.18632/aging.202441How to Cite
Abstract
Patients with Werner syndrome present with diverse signs of aging that begin in adolescence. A Japanese nationwide survey was conducted to establish a registry that could clarify the disease profile of patients with Werner syndrome. The questionnaires were sent to 7888 doctors. The survey identified 116 patients diagnosed with Werner syndrome based on the diagnosis criteria. Forty patients were enrolled in the registry. Data on clinical symptoms, treatment information, and laboratory examination from patients who provided informed consent were collected. The data at enrollment were analyzed. The patients’ average age at enrollment was 50.1±7.5 years. The mean onset age was 26.1±9.5 years, but the mean age at diagnosis was 42.5±8.6 years. Average height and weight of the study patients were lower than those of Japanese individuals. Almost all patients experienced hair change and cataracts. More than 60% of patients presented with glycolipid abnormalities. Overall, 15% of patients had a history of foot amputation. Approximately 30% of the patients’ parents had a consanguineous marriage. The average grip strength, walking speed, and skeletal muscle mass index met the diagnostic criteria for sarcopenia. The registry revealed that there are opportunities for early diagnosis and intervention; therefore, sensitization about the disease is needed.